Background: Hydrometrocolpos is a rare condition. Hydrometrocolpos is a cystic dilatation of the uterovaginal with fluid accumulation due to a combination of stimulation of secretory glands of the reproductive tract and vaginal obstruction such as imperforate hymen, transverse vaginal septum or vaginal atresia. Purpose: In this paper, the researchers would report the rare case of hydrometrocolpos in the newborns with the imperforate hymen. Method: The researchers report a case a 24-year-old primigravida at term was referred to the hospital with the suspected fetal congenital anomalies. It shows prenatal fetal ultrasonography with intra-abdominal cystic mass. Then, a female neonate was delivered vaginally with a good Apgar score. Result: Physical examination of the neonate revealed a cystic mass intralabial caused by the bulging membrane in the vaginal introitus. Ultrasonography and magnetic resonance imaging postnatal further defined a cystic mass in the pelvic extending caudally into the vagina and mild left hydronephrosis which is the result of mass compression. Therefore, the diagnosis of hydrometrocolpos with the imperforate hymen was established. Conclusion: The treatment by hymenotomy and marsupialization to the evacuated hydrometrocolpos was performed. The infants are recovered fully after the treatment and show postoperative ultrasonography resolution of hydrometrocolpos and hydronephrosis.

• Adaletli, I., Ozer, H., Kurugoglu, S., Emir, H., & Madazli, R. (2007). Congenital imperforate hymen with hydrocolpos diagnosed using prenatal MRI. American Journal of Roentgenology, 189(1), W23-W25.
• Azinar, A. D., Annas, J. Y., Primariawan, R. Y., & Hardianto, G. (2017). Treatment of cervical agenesis with minimally invasive therapy: Case report. Gynecology and minimally invasive therapy, 6(4), 202-204.
• Bableshwar, A., Al Amer, S., & Kalis, N. N. (2018). Congenital Heart Diseases in Noonan’s Syndrome-Mitral Valve Anomalies: Important Cause of Left Ventricular Outflow Tract Obstruction. Bahrain Medical Bulletin, 40(4), 215-218.
• Eksioglu, A. S., Maden, H. A., Cinar, G., & Yildiz, Y. T. (2012). Imperforate hymen causing bilateral hydroureteronephrosis in an infant with bicornuate uterus. Case reports in urology, 2012.
• Gupta, M., Bajwa, S. J. S., & Gupta, M. (2014). Diagnostic dilemmas in management of neonatal hydrometrocolpos: A crucial role of magnetic resonance imaging. International Journal of Health & Allied Sciences, 3(4), 251.
• GÜRATEfi, B., Kazez, A., Sapmaz, E., Bulgan, E., & Yayla, M. (2000). Prenatal diagnosis of congenital imperforate hymen.
• Karteris, E., Foster, H., Karamouti, M., & Goumenou, A. (2010). Congenital imperforate hymen with hydrocolpos and hydronephrosis associated with severe hydramnios and increase of maternal ovarian steroidogenic enzymes. Journal of Pediatric and Adolescent Gynecology, 23(3), 136-141.
• Rouma, B., Aldrink, J., Finkelstei, n. J, Ginsburg, H.(2011). Hydrometrocolpos. In: Ameh E, Bickler S, Lakhoo A, Nwomeh B, Poenaru D, editors. Pediatric Surgery: A Comprehensive Text for Africa [Internet]. 1st ed. Seattle: The Global Help Organization; p. 672–7. Available from: https://global-help.org/products/paediatric_surgery_a_comprehensive_text_for_africa/
• Smit-Fun, V. M., & Buhre, W. F. (2019). Heart failure in adult patients with congenital heart disease. Anesthesiology clinics, 37(4), 751-768.
• Toor, R. A., Sayyad, M. H., Nasr, N., Sajjad, S., Shah, S. A. A., & Manzoor, T. (2016). Efficiency Enhancement of Dye Sensitized Solar Cells with a Low Cost Co-Adsorbant in N719 Dye. International Journal of Sustainable Energy and Environmental Research, 5(3), 46-50
• Tseng, J. J., Ho, J. Y. P., Chen, W. H., & Chou, M. M. (2008). Prenatal diagnosis of isolated fetal hydrocolpos secondary to congenital imperforate hymen. Journal of the Chinese Medical Association, 71(6), 325-328.
• Vitale, V., Cigliano, B., & Vallone, G. (2013). Imperforate hymen causing congenital hydrometrocolpos. Journal of ultrasound, 16(1), 37-39.

This is an open access article distributed under the Creative Commons Attribution License which permits unrestricted use, distribution, and reproduction in any medium, provided the original work is properly cited.